Two-stage surgical management of horseshoe lung associated with congenital pulmonary airway malformation in a neonate: A case report

Authors

DOI:

https://doi.org/10.47338/jns.v12.1215

Keywords:

Horseshoe lung, Congenital pulmonary airway malformations, Neonate

Abstract

Background: Horseshoe lung is a rare congenital malformation, and even rarer is its association with congenital pulmonary airway malformations.

Case Presentation: We report a case of horseshoe lung associated with congenital pulmonary airway malformation (Stocker type 2) who underwent surgical management in two stages. The patient had a right posterolateral thoracotomy with lower right lobectomy at 14 days of life, followed by a left posterolateral thoracotomy with lower left lobectomy at 7 months of age. He is doing fine after both surgeries and follow-up visits are ongoing.

Conclusion: The treatment of horseshoe lung should be individualized, surgical management is an effective option and the two-stage approach in neonates would reduce the risk of the simultaneous bilateral procedure.

Downloads

Download data is not yet available.

Metrics

Metrics Loading ...

References

Mfingwana L, Goussard P, Andronikou S, Morrison J. Horseshoe lung in a young child at Tygerberg Hospital, South Africa. Afr J Thorac Crit Care Med. 2021; 24:171?3. https://doi.org/10.7196/ajrccm.2021.v27i4.138.

Gonen K, Canitez Y, Bostan O, Yazici Z. Horseshoe lung associated with Scimitar syndrome. BMJ Case Rep. 2019; 12. https://doi.org/10.1136/bcr-2014-204389.

Cerron-Vela C, Youssef F, Cowan KN, Davila J. Is horseshoe lung a component of VACTERL spectrum? Case report and review of literature. Radiol Case Rep. 2022; 17:1558?62. https://doi.org/10.1016/j.radcr.2022.02.014.

Kersten CM, Hermelijn SM, Mullassery D, Muthialu N, Cobanoglu N, Gartner S, et al. The management of asymptomatic congenital pulmonary airway malformation: Results of a European Delphi survey. Children. 2022; 9:1153. https://doi.org/10.3390/children9081153.

Duc NM, My TT, Huong TQ, Bang MT. Two rare cases of horseshoe lung with scimitar syndrome in Vietnam. Resp Med Case Rep. 2021; 32:101357. https://doi.org/10.1016/j.rmcr.2021.101357.

Salerno M, Sessa F, Cocimano G, Roccuzzo S, Esposito M, Pomara C. Congenital cystic adenomatoid malformation (CCAM) type II: A rare case of sudden infant death. Children. 2022; 9:1830. https://doi.org/10.3390/children9121830.

Strumi??o B, J??wiak A, Pa?ka A, Szaflik K, Piaseczna-Piotrowska A. Congenital cystic adenomatoid malformation ? diagnostic and therapeutic procedure: 8-year experience of one medical centre. Polish J Cardio-Thoracic Surg. 2018; 15:10?7. https://doi.org/10.5114/kitp.2018.74669.

Febriani AD, Shoraya NS, Alasiry E. Congenital cystic adenomatoid malformations type 1: Case report. Open Acc Macedonian J Med Sci. 2022; 10:123?5. https://doi.org/10.3889/oamjms.2022.8539.

Downard CD, Calkins CM, Williams RF, Renaud EJ, Jancelewicz T, Grabowski J, et al. Treatment of congenital pulmonary airway malformations: A systematic review from the APSA outcomes and Evidence-Based Practice Committee. Pediatr Surg Int. 2017; 33:939?53. https://doi.org/10.1007/s00383-017-4098-z.

Morini F, Zani A, Conforti A, van Heurn E, Eaton S, Puri P, et al. Current management of congenital pulmonary airway malformations: A ?European Pediatric Surgeons' Association? survey. Eur J Pediatr Surg. 2017; 28:001?5. https://doi.org/10.1055/s-0037-1604020.

Hawass ND, Badawi MG, Fatani JA, Meshari AA, Edrees YB. Horseshoe lung with multiple congenital anomalies. Case report and review of the literature. Acta Radiol. 1987; 28:751-4.

Published

2023-04-21

How to Cite

1.
Polit-Guerrero V, Andrade-Montesdeoca J, Fabre-Parrales E, Salinas-Salinas V, Acosta-Farina D. Two-stage surgical management of horseshoe lung associated with congenital pulmonary airway malformation in a neonate: A case report. J Neonatal Surg [Internet]. 2023Apr.21 [cited 2023Sep.25];12:14. Available from: https://www.jneonatalsurg.com/ojs/index.php/jns/article/view/1215

Most read articles by the same author(s)