Two-stage surgical management of horseshoe lung associated with congenital pulmonary airway malformation in a neonate: A case report
DOI:
https://doi.org/10.47338/jns.v12.1215Keywords:
Horseshoe lung, Congenital pulmonary airway malformations, NeonateAbstract
Background: Horseshoe lung is a rare congenital malformation, and even rarer is its association with congenital pulmonary airway malformations.
Case Presentation: We report a case of horseshoe lung associated with congenital pulmonary airway malformation (Stocker type 2) who underwent surgical management in two stages. The patient had a right posterolateral thoracotomy with lower right lobectomy at 14 days of life, followed by a left posterolateral thoracotomy with lower left lobectomy at 7 months of age. He is doing fine after both surgeries and follow-up visits are ongoing.
Conclusion: The treatment of horseshoe lung should be individualized, surgical management is an effective option and the two-stage approach in neonates would reduce the risk of the simultaneous bilateral procedure.
Downloads
Metrics
References
Mfingwana L, Goussard P, Andronikou S, Morrison J. Horseshoe lung in a young child at Tygerberg Hospital, South Africa. Afr J Thorac Crit Care Med. 2021; 24:171?3. https://doi.org/10.7196/ajrccm.2021.v27i4.138.
Gonen K, Canitez Y, Bostan O, Yazici Z. Horseshoe lung associated with Scimitar syndrome. BMJ Case Rep. 2019; 12. https://doi.org/10.1136/bcr-2014-204389.
Cerron-Vela C, Youssef F, Cowan KN, Davila J. Is horseshoe lung a component of VACTERL spectrum? Case report and review of literature. Radiol Case Rep. 2022; 17:1558?62. https://doi.org/10.1016/j.radcr.2022.02.014.
Kersten CM, Hermelijn SM, Mullassery D, Muthialu N, Cobanoglu N, Gartner S, et al. The management of asymptomatic congenital pulmonary airway malformation: Results of a European Delphi survey. Children. 2022; 9:1153. https://doi.org/10.3390/children9081153.
Duc NM, My TT, Huong TQ, Bang MT. Two rare cases of horseshoe lung with scimitar syndrome in Vietnam. Resp Med Case Rep. 2021; 32:101357. https://doi.org/10.1016/j.rmcr.2021.101357.
Salerno M, Sessa F, Cocimano G, Roccuzzo S, Esposito M, Pomara C. Congenital cystic adenomatoid malformation (CCAM) type II: A rare case of sudden infant death. Children. 2022; 9:1830. https://doi.org/10.3390/children9121830.
Strumi??o B, J??wiak A, Pa?ka A, Szaflik K, Piaseczna-Piotrowska A. Congenital cystic adenomatoid malformation ? diagnostic and therapeutic procedure: 8-year experience of one medical centre. Polish J Cardio-Thoracic Surg. 2018; 15:10?7. https://doi.org/10.5114/kitp.2018.74669.
Febriani AD, Shoraya NS, Alasiry E. Congenital cystic adenomatoid malformations type 1: Case report. Open Acc Macedonian J Med Sci. 2022; 10:123?5. https://doi.org/10.3889/oamjms.2022.8539.
Downard CD, Calkins CM, Williams RF, Renaud EJ, Jancelewicz T, Grabowski J, et al. Treatment of congenital pulmonary airway malformations: A systematic review from the APSA outcomes and Evidence-Based Practice Committee. Pediatr Surg Int. 2017; 33:939?53. https://doi.org/10.1007/s00383-017-4098-z.
Morini F, Zani A, Conforti A, van Heurn E, Eaton S, Puri P, et al. Current management of congenital pulmonary airway malformations: A ?European Pediatric Surgeons' Association? survey. Eur J Pediatr Surg. 2017; 28:001?5. https://doi.org/10.1055/s-0037-1604020.
Hawass ND, Badawi MG, Fatani JA, Meshari AA, Edrees YB. Horseshoe lung with multiple congenital anomalies. Case report and review of the literature. Acta Radiol. 1987; 28:751-4.

Published
How to Cite
Issue
Section
License
Copyright (c) 2023 Veronica Polit-Guerrero, Jimmy Andrade-Montesdeoca, Ernesto Fabre-Parrales, Vicente Salinas-Salinas, Daniel Acosta-Farina

This work is licensed under a Creative Commons Attribution 4.0 International License.
You are free to:
- Share — copy and redistribute the material in any medium or format
- Adapt — remix, transform, and build upon the material for any purpose, even commercially.
Terms:
- Attribution — You must give appropriate credit, provide a link to the license, and indicate if changes were made. You may do so in any reasonable manner, but not in any way that suggests the licensor endorses you or your use.
- No additional restrictions — You may not apply legal terms or technological measures that legally restrict others from doing anything the license permits.