Two-stage surgical management of horseshoe lung associated with congenital pulmonary airway malformation in a neonate: A case report

Veronica Polit-Guerrero; Jimmy Andrade-Montesdeoca; Ernesto Fabre-Parrales; Vicente Salinas-Salinas; Daniel Acosta-Farina

doi:10.47338/jns.v12.1215

Authors

Veronica Polit-Guerrero Catholic University of Santiago de Guayaquil / Dr. Roberto Gilbert Elizalde Childrens Hospital https://orcid.org/0000-0002-2060-6590
Jimmy Andrade-Montesdeoca Catholic University of Santiago de Guayaquil / Dr. Roberto Gilbert Elizalde Childrens Hospital https://orcid.org/0000-0002-3748-4585
Ernesto Fabre-Parrales Dr. Roberto Gilbert Elizalde Childrens Hospital https://orcid.org/0000-0002-6619-4819
Vicente Salinas-Salinas Dr. Roberto Gilbert Elizalde Childrens Hospital https://orcid.org/0000-0002-0007-3168
Daniel Acosta-Farina Dr. Roberto Gilbert Elizalde Childrens Hospital / Catholic University of Santiago de Guayaquil https://orcid.org/0000-0002-9655-2824

DOI:

https://doi.org/10.47338/jns.v12.1215

Keywords:

Horseshoe lung, Congenital pulmonary airway malformations, Neonate

Abstract

Background: Horseshoe lung is a rare congenital malformation, and even rarer is its association with congenital pulmonary airway malformations.

Case Presentation: We report a case of horseshoe lung associated with congenital pulmonary airway malformation (Stocker type 2) who underwent surgical management in two stages. The patient had a right posterolateral thoracotomy with lower right lobectomy at 14 days of life, followed by a left posterolateral thoracotomy with lower left lobectomy at 7 months of age. He is doing fine after both surgeries and follow-up visits are ongoing.

Conclusion: The treatment of horseshoe lung should be individualized, surgical management is an effective option and the two-stage approach in neonates would reduce the risk of the simultaneous bilateral procedure.

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