A remarkable case of intrauterine intussusception, ileal atresia, and complicated meconium ileus: A case report
DOI:
https://doi.org/10.47338/jns.v13.1243Keywords:
Fetal ascites, Ileal atresia, Cystic fibrosisAbstract
Background: Intrauterine intussusception, although very rare (<2%), is a potential cause of intestinal atresia. It usually manifests as bowel obstruction during the first hours or days of life.
Case Presentation: We report a case with fetal ascites prompting early Cesarean section, with subsequent percutaneous abdominal drainage and laparotomy. Intraoperative findings showed meconium peritonitis and type IIIa ileal atresia with intussusception of the distal part, with the necrosed intussusceptum likely causing perforation and ileal atresia; in addition, the distal ileum demonstrated signs of meconium ileus. After ileostomy creation, the postoperative course was uneventful. Cystic fibrosis was excluded via a sweat test.
Conclusion: Prompt diagnosis and management of neonatal intestinal obstruction secondary to the unusual combination of fetal ascites, intussusception, complicated meconium ileus, and ileal atresia results in a favorable outcome.
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Dalla Vecchia LK, Grosfeld JL, West KW, Rescorla FJ, Scherer LR, Engum SA. Intestinal Atresia and Stenosis: A 25-Year Experience with 277 Cases. Arch Surg.1998;133(5):490–7.
Yang JI, Kim HS, Chang KH, Hong J, Joo HJ, Ryu HS. Intrauterine intussusception presenting as fetal ascites at prenatal ultrasonography. Am J Perinatol, 2004;21(04):241-6.
Wang NL, Yeh ML, Chang PY, Sheu JC, Chen CC, Lee HC, et al. Prenatal and neonatal intussusception. Ped Surg Int.1998;13:232-6.
Chouikh T, Charieg A, Mrad C, Ghorbel S, Saada S, Benkhalifa S, et al. Intestinal atresia caused by intrauterine intussusception: A case report and literature review. J Pediatr Surg Case Rep.2014;2:203-5.
Kim MW, Bae HS, Boo YJ, Lee JH, Hong SC, Oh MJ, et al. Meconium Peritonitis Associated with Intrauterine Intussusception: A Case Report. Kor J Ultrasound Obs Gyn. 2011;13(1):23-7.
Joshi SB, Kinhal V, Desai M, Choudhari FUR. A rare case of jejunal atresia due to intrauterine intussusception. J Clin Diagn Res. 2015;9(9), PD30.
Shyu MK, Shih JC, Lee CN, Hwa HL, Chow SN, Hsieh FJ. Correlation of prenatal ultrasound and postnatal outcome in meconium peritonitis. Fetal Diagn Ther. 2003;18(4):255-61.
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Copyright (c) 2023 Jonathan Hencke, Oliver Diez, Steffan Loff
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